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. 2023 May 3;43(5):369–377. doi: 10.1007/s40261-023-01270-x

Table 1.

Prescribing summary of olipudase alfa (Xenpozyme®) in the treatment of non-CNS manifestations of acid sphingomyelinase deficiency in the EU [14] and USA [15]. Consult local prescribing information for further details

What is the approved indication of olipudase alfa?
 EU: treatment of non-CNS manifestations of ASMD in adult and paediatric patients with type A/B or type B
 USA: treatment of non-CNS manifestations of ASMD in adult and paediatric patients
How is olipudase alfa available and how should it be stored?
 Available as: lyophilised powder in a 20 mg single-dose vial for reconstitution and dilution for intravenous infusion
 Storage: refrigerate (do not freeze) original product at 2–8 °C; refrigerate reconstituted vials or diluted solutions (if not used immediately) at 2–8 °C for up to 24 h or store at room temperature (20–25 °C) for up to 12 h
What is the recommended administration regimen and method for olipudase alfa?
 Dose-escalation phase Adults: 0.1, 0.3, 0.3, 0.6, 0.6, 1 and 2 mg/kg at weeks 0, 2, 4, 6, 8, 10, and 12, respectively
Paediatric patients: 0.03, 0.1, 0.3, 0.3, 0.6, 0.6, 1 and 2 mg/kg at weeks 0, 2, 4, 6, 8, 10, 12 and 14, respectively
 Maintenance dose 3 mg/kg every 2 weeks from week 14 in adults and week 16 in paediatric patients
 Administration method Increase infusion ratea incrementally in four steps and only in the absence of infusion-associated reactions, with the first three steps lasting for 20 min

Adjust infusion volumesa patients with acid sphingomyelinase

based on patient age and/or body weight

How should olipudase alfa be used in special populations?
 Patients with abnormal kidney function No dosage adjustment required
 Patients with abnormal liver function No dosage adjustment required
 Elderly patients No dosage adjustment required (based on limited data)
 Breastfeeding patients It is not known whether olipudase alfa is excreted in human milk, but a risk to newborns cannot be excluded based on animal studies
Discontinue breastfeeding or treatment based on benefits of breastfeeding for infant versus mother’s clinical need for treatment
What other special warnings/precautions pertain to the use of olipudase alfa?
 Hypersensitivity reactions including anaphylaxis, infusion-associated reactions Consider premedications (antihistamines, antipyretics, corticosteroids)
Severe reaction: discontinue treatment and initiate appropriate medical treatment
Mild or moderate reaction: adjust infusion rate, temporarily withhold infusion, or adjust dosage
 Elevated transaminases Monitor ALT and AST levels before and during treatment; adjust dosage based on transaminase levels or withhold treatment until levels return to baseline value
 Risks during pregnancy Do not initiate or escalate dosage at any time during pregnancy; base maintenance dosing decision on patient’s benefit-risk profile
Advise women of reproductive potential to use effective contraception during and for 14 days after the last dose of treatment

ALT alanine aminotransferase, ASMD acid sphingomyelinase deficiency, AST aspartate aminotransferase, CNS central nervous system

aConsult local prescribing information for the recommended infusion rates and volumes