Clinical images show oral ulceration and limitation in tongue protrusion
(Panel A); spreading waxy, hypopigmented lesions on the back and waxy
hypopigmented “tank top” sign on the chest (Panels B and C); and
ulcerations with articular ankylosis of the legs and arms (Panels D and E).
Histologic sections of skin-biopsy samples show prominent inflammation (Panel F)
and dermal thickening and hyalinization of morphea (Panel G). Images are shown
of immunohistochemical staining for smooth-muscle action (Panel H) and CD3
(Panel I) in skin-biopsy samples before use of ruxolitinib. Family pedigrees
(Panel J) are shown, with probands indicated by arrows. Circles represent female
family members, squares male family members, and solid symbols persons who have
received a diagnosis of DPM. Grey shading indicates persons with the
STAT4 variants but with milder symptoms. The genotype at
the specified locus is indicated under each person. A linear protein model
(Panel K) shows the approximate locations of the identified variants in the SRC
homology 2 (SH2) domain. CC denotes coiled-coil domain, DBD DNA-binding domain,
LD linker domain, N the N-terminal domain, TAD transactivation domain, and Y the
phosphotyrosyl-tail segment.