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. Author manuscript; available in PMC: 2024 Apr 1.
Published in final edited form as: Acta Neuropathol. 2023 Feb 17;145(4):479–496. doi: 10.1007/s00401-023-02551-7

Table 2. Variability of sarcolemmal protein reduction in several individuals with DTNA-related muscular dystrophy with the same variant DTNA c.1585G>A; p.Glu529Lys (family A) and with variant c.1567_1587del21; p.Gln523_Glu529del7 (family C).

A.III.2 A.III.1 A.II.7 A.II.2 C.II.1
Beta-spectrin ++++ +++ ++++ ++++
DYS1 ++ ++ ++ +++ ++
DYS2 +++ + ++++ ++ +
DYS3 + ++++ + +
Beta-dystroglycan ++++ ++ ++++ ++ +++
Alpha-dystroglycan (VIA4) ++ + ++++ ++
Alpha-dystroglycan (IIH6) + + +++ ++ +++
Alpha-sarcoglycan +++ ++ + +
Beta-sarcoglycan + ++ ++ ++ +
Delta-sarcoglycan +++ + +++ +
Gamma-sarcoglycan ++ + +++ + +
Alpha-dystrobrevin +++ ++ + + +

++++ = normal staining; +++ = mildly diminished; ++ = moderately diminished; + = severely diminished; − = absent.