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. 2025 Sep 24;17:56. doi: 10.1186/s11689-025-09645-1

Table 1.

MED13L variants of the in-person cohort

ID Variant (NM_015335.4) Type Inheritance Classification Age at Diagnosis
F1S1a c.5990dup,p.Leu1997Phefs*19 LoF De novo Pathogenic 3y8m
F2S1 c.401dup,p.Met135Asnfs*3 LoF De novo Pathogenic 2y5m
F3S1a c.5471del,p.Asn1824Metfs*28 LoF Inherited—Paternal (somatic mosaic; 7% of reads) Pathogenic 3y8m
F4S1a c.2597C > T,p.Pro866Leu Missense De novo Pathogenic 0y7m
F5S1a arr[GRCh37] 12q24.21(116,519,929–116,553,225) × 1 Deletion Unknown Pathogenic 17y6m
F6S1a c.6556C > T,p.Gln2186* LoF De novo Likely Pathogenic 2y11m
F7S1a c.3469C > T,p.Gln1157* LoF De novo Pathogenic 2y9m
F8S1a arr[GRCh37] 12q24.21(116,673,140–116,676,995) × 1 Deletion De novo (germline mosaicism inferred) Pathogenic 4y10m
F8S2a arr[GRCh37] 12q24.21(116,673,140–116,676,995) × 1 Deletion De novo (germline mosaicism inferred) Pathogenic 6y6m
F9S1 c.4077G > A,p.Trp1359* LoF De novo Pathogenic 5y8m
F10S1 arr[GRCh37] 12q24.21(116476163_116619234) × 1 Deletion De novo Pathogenic 1y6m
F11S1a arr[hg18] 12q24.21(114,895,862–115,110,038) × 1 Deletion De novo Pathogenic 3y0m
F12S1a c.4609C > T,p.Gln1537* LoF De novo Pathogenic 1y5m
F13S1a c.4403dup,p.Thr1470Asnfs*9 LoF De novo Pathogenic 6y7m
F14S1a c.1690C > T,p.Arg564* LoF De novo (germline mosaicism inferred) Pathogenic 5y0m
F14S2a c.1690C > T,p.Arg564* LoF De novo (germline mosaicism inferred) Pathogenic 1y10m
F15S1 c.6488C > T,p.Ser2163Leu Missense De novo Likely Pathogenic 13y2m

Abbreviations: LoF loss of function, y years, m months

aIndividuals also completed some aspects of Simons Searchlight virtual assessment protocol