Skip to main content
. 2001 Nov 8;4(2):94–106. doi: 10.1186/ar396

Table 1.

Selected genes causal to skeletal diseases and disorders

OMIM # Gene name Gene symbol Diseases and disorders
114290 Sry-related HMG-box gene 9 SOX9 Acampomelic campomelic dysplasia
Campomelic dysplasia
Campomelic dysplasia with autosomal sex reversal
120110 Collagen, type X alpha-1 COL10A1 Metaphyseal chondrodysplasia, Schmid type
Spondylometaphyseal dysplasia, Japanese type
120140 Collagen, type II alpha-1 COL2A1 Achondrogenesis, type II
Achondrogenesis-hypochondrogenesis, type II
Hypochondrogenesis
Kniest dysplasia
Osteoarthritis with mild chondrodysplasia
Spondyloepimetaphyseal dysplasia, Strudwick type
Spondyloepiphyseal dysplasia, various types
Spondylometaphyseal dysplasia, congenital type
Spondyloperipheral dysplasia
Stickler syndrome, type I
Wagner syndrome
120150 Collagen, type I alpha-1 COL1A1 Ehlers–Danlos syndrome, types I and VIIA
Osteogenesis imperfecta, types I, II, III, and IV
120160 Collagen, type I alpha-2 COL1A2 Ehlers–Danlos syndrome, type VII-B
Osteogenesis imperfecta, types II, III, and IV
Osteogenesis imperfecta/Ehlers–Danlos crossover syndrome
Marfan syndrome, atypical
120180 Collagen, type III alpha-1 COL3A1 Arterial and aortic aneurysms
Ehlers–Danlos syndrome, types III and IV
120190 Collagen, type V alpha-2 COL5A2 Ehlers–Danlos syndrome, types I and II
120215 Collagen, type V alpha-1 COL5A1 Ehlers–Danlos syndrome, types I, II, and mixed type
120260 Collagen, type IX alpha-2 COL9A2 Epiphyseal dysplasia, multiple, type 2
Intervertebral disc disease
120270 Collagen, type IX alpha-3 COL9A3 Epiphyseal dysplasia, multiple, type 3
Epiphyseal dysplasia, multiple, with myopathy
120280 Collagen, type XI alpha-1 COL11A1 Stickler syndrome, type II
Marshall syndrome
120290 Collagen, type XI alpha-2 COL11A2 Sensorineural deafness, autosomal dominant nonsyndromic
Otospondylomegaepiphyseal dysplasia
Stickler syndrome, type III
Weissenbacher–Zweymuller syndrome
120360 Matrix metalloproteinase 2 MMP2 Osteolysis, idiopathic, Saudi type
121050 Fibrillin 2 FBN2 Contractural arachnodactyly, congenital
123101 Muscle segment homeobox 2 MSX2 Craniosynostosis, Boston-type
Parietal foramina 1
125505 Deoxyribonuclease I DNASE1 Systemic lupus erythematosus susceptibility
133700 Exostosin 1 EXT1 Exostoses, multiple, type 1
Chondrosarcoma
133701 Exostosin 2 EXT2 Exostoses, multiple, type II
134797 Fibrillin 1 FBN1 Marfan syndrome, various types
Ectopia lentis, familial
Marfanoid skeletal syndrome
Mass syndrome
Shprintzen-Goldberg syndrome
134934 Fibroblast growth factor receptor 3 FGFR3 Achondroplasia
Crouzon syndrome with acanthosis nigricans
Hypochondroplasia
Muenke syndrome
Multiple myeloma
Saddan dysplasia
Thanatophoric dysplasia, types I and II
136350 Fibroblast growth factor receptor 1 FGFR1 Pfeiffer syndrome
139250 Growth hormone 1 GH1 Growth hormone deficiency
Isolated growth hormone deficiency, type I
Kowarski syndrome
139320 Guanine nucleotide-binding protein, GNAS1 Mccune–Albright syndrome
 alpha-stimulating activity polypeptide 1 Albright hereditary osteodystrophy
Pituitary adenoma, ACTH-secreting
142461 Heparan sulfate proteoglycan HSPG2 Schwartz–Jampel syndrome, type 1
 of basement membrane, perlecan Dyssegmental dysplasia, Silverman–Handmaker type
142958 Homeobox A11 HOXA11 Radioulnar synostosis with amegakaryocytic thrombocytopenia
147620 Interleukin 6 IL6 Interleukin 6 polymorphism associated with systemic onset
 juvenile rheumatoid arthritis
154870 Matrix gamma-carboxyglutamic MGP Keutel syndrome
 acid protein
156845 Microphthalmia-associated MITF Waardenburg syndrome, type IIA
 transcription factor Tietz albinism–deafness syndrome
157660 Mitochondrial RNA-processing RMRP Cartilage–hair hypoplasia
 endoribonuclease (RNA component of)
168450 Parathyroid hormone PTH Hypoparathyroidism
168468 Parathyroid hormone receptor 1 PTHR1 Metaphyseal chondrodysplasia, Murk Jansen type
Chondrodysplasia, Blomstrand type
176943 Fibroblast growth factor receptor 2 FGFR2 Apert syndrome
Beare–Stevenson cutis gyrata syndrome
Craniosynostosis, nonsyndromic unicoronal
Crouzon syndrome
Jackson–Weiss syndrome
Pfeiffer syndrome
Saethre–Chotzen syndrome
190180 Transforming growth factor, beta-1 TGFB1 Camurati–Engelmann disease
193500 Paired box gene 3 PAX3 Waardenburg syndrome, types I, II, and III
Waardenburg syndrome with meningomyelocele
Rhabdomyosarcoma, alveolar
Craniofacial–deafness–hand syndrome
203500 Homogentisate 1,2-dioxygenase HGD Alkaptonuria
217000 Complement component 2 C2 Complement component 2 deficiency
222600 Solute carrier family 26, member 2 SLC26A2 Achondrogenesis, type IB
Atelosteogenesis, type II
Diastrophic dysplasia
249100 Familial Mediterranean fever gene MEFV Familial Mediterranean fever
277900 ATPase, Cu(2+)-transporting, ATP7B Wilson Disease
 beta polypeptide
300202 Sedlin SEDL Spondyloepiphyseal dysplasia, late
300300 Bruton agammaglobulinemia BTK Agammaglobulinemia, X-linked associated with
 tyrosine kinase  septic arthritis
308000 Hypoxanthine guanine HPRT1 Gout, HPRT-related
 phosphoribosyltransferase 1 Lesch–Nyhan syndrome
311850 Phosphoribosylpyrophosphate PRPS1 Gout, PRPS-related
 synthetase I
312865 Short stature homeobox SHOX Short stature, idiopathic
Leri–Weill dyschondrosteosis
Langer mesomelic dysplasia
600211 Runt-related transcription factor 2 RUNX2 Cleidocranial dysplasia
600310 Cartilage oligomeric matrix protein COMP Epiphyseal dysplasia
Pseudoachondroaplasia
600725 Sonic hedgehog SHH Holoprosencephaly 3
600726 Indian hedgehog IHH Brachydactyly type A1
600856 Cyclin-dependent kinase inhibitor 1C CDKN1C Beckwith–Wiedemann syndrome
600946 Growth hormone receptor GHR Laron syndrome
Short stature, autosomal dominantand idiopathic
601105 Cathepsin K CTSK Pycnodysostosis
601146 Growth/differentiation factor 5 GDF5 Acromesomelic dysplasia, Hunter–Thompson type
Brachydactyly, type C
Chondrodysplasia, Grebe type
601199 Calcium-sensing receptor CASR Hypercalciuric hypercalcemia
Hypercalciuric hypocalcemia
Hyperparathyroidism
Hypocalcemia
Hypocalciuric hypercalcemia
Hypoparathyroidism, various types
601309 Patched PTCH Basal cell nevus syndrome
Basal cell carcinoma, sporadic
601769 Vitamin D receptor VDR Vitamin D-resistant rickets, type II
602109 Matrilin 3 MATN3 Multiple epiphyseal dysplasia
602337 Receptor tyrosine kinase-like ROR2 Brachydactyly, type B1
 Orphan receptor 2 Robinow syndrome, autosomal recessive
602365 Cathepsin C CTSC Papillon–Lefevre syndrome
Haim–Munk syndrome
602727 Chloride channel 7 CLCN7 Osteopetrosis, Autosomal Recessive, Infantile Malignant
602991 Noggin NOG Symphalangism, proximal
Multiple synostoses syndrome 1
603400 Wnt1-inducible signaling WISP3 Arthropathy, progressive pseudorheumatoid of childhood
 pathway protein 3
603499 Tumor necrosis factor receptor TNFRSF11A Expansile osteolysis, familial
 superfamily, 11A Paget disease of bone 2
604142 Tyro protein tyrosine TYROBP Polycystic lipomembranous osteodysplasia with sclerosing
 kinase-binding protein  leukoencephalopathy
604283 Proteoglycan 4 PRG4 Camptodactyly–arthropathy–coxa vara–pericarditis syndrome
604592 T cell immune regulator 1 TCIRG1 Osteopetrosis, autosomal recessive
604831 Ellis–Van Creveld syndrome gene EVC Ellis-Van Creveld syndrome
Weyers acrodental dysostosis
605145 Ank ANKH Craniometaphyseal dysplasia, autosomal dominant
605380 Fibroblast growth factor 23 FGF23 Hypophosphatemic rickets, autosomal dominant
605420 Aristaless-like 4, ALX4 Parietal foramina 2
605740 Sclerostin SOST Sclerosteosis

Mutations in a number of genes have been shown to cause congenital skeletal disorders, often with defects in cartilage formation as the primary basis. Others predispose the individual towards skeletal diseases such as arthritis. The completed sequence of the human genome opens the door for rapid identification of additional genetic mutations associated with human diseases and disorders. Functional genomics and the characterization of molecular mechanisms bridging genotypes to phenotypes are our challenges to realize solutions for the prevention, detection, diagnosis and therapy of these diseases and disorders. Data extracted from Online Mendelian Inheritance in Man (OMIM) [113].