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. 2006 Apr 24;55(12):1781–1788. doi: 10.1136/gut.2005.090159

Table 3 Mismatch repair gene mutation carriers their cancer history and family history, and the results of immunohistochemistry and microsatellite instability analysis.

Patient number, sex Gene / exon DNA change/ protein change Cancer/ age at diagnosis (years) MSI H/L IHC: presence of FH/ACII
MLH1 MSH2 MSH6
1. Male MLH1 18del( CRC/45 ND ND ND ND +/−
1 GTTATTCGGCGGCTGGA) CRC/49 H + ND P: CRC 42
Gly6FsX29 STC/53 L ND ND ND
2. Female MLH1 c. 380G→A CRC/13 H + + +/−
4 SD destroyed P: CRC/27
3. Female MLH1 c. 860_861insA CRC/46 H + + +/+
10 p. Asn287fsX306 CRC/46 ND ND ND ND M: CRC/80
4. Female MLH1 Del exon 16 CRC/50 H + + +/+
16 EC/50 H ND ND ND M: EC/50 S: CRC/48
5. Male MLH1 Del exon 16 CRC/44 H NI + + −/−
16
6. Male MLH1 Del exon 16 CRC/41 ND ND ND ND −/−
16 CRC/48 ND ND ND ND
CRC/48 H + + +
7. Female MLH1 c. 1852–1854delGAA CRC/25 H + ND +/−
16 p. Lys618del P: CRC/36
8. Female* MLH1 c. 1946delC EC/49 H + NI +/+
17 p. Pro649fsX661 CRC/53 H + + P: CRC/72 S: EC/?
9. Female MSH2 Del exon 1–3 BLC/56 H + NI −/−
1–3 2xCRC/58 H +
EC/59 L +
10. Male MSH2 Del exon 2 CRC/46 H ND ND ND +/+
2 Out of frame del M: EC/59
11. Female MSH2 Del exon 2 EC/42 H + +/+
2 Out of frame del CRC/47 H + M: EC/39
12. Female MSH2 c. 759delG OC/42 ND ND ND ND −/−
4 p. Met253fsX273 CRC/48 H + ND
CRC/62 ND ND ND ND
CRC/65 ND ND ND ND
13. Male MSH2 Del exon 4–7 CRC/38 ND ND ND ND +/−
4–7 Out of frame del CRC/50 H + + P: STC/43
14. Female MSH2 Del exon 11–14 EC/48 H + +/+
11–14 In frame deletion of 183 amino acids CRC/54 H + M: EC/43
15. Female MSH2 c. 1835C→G CRC/31 ND ND ND ND +/+
12 p. Ser612stop CRC/53 H + NI P: CRC/51
16. Female MSH2 c. 1861C→T CRC/29 H + ND +/−
12 p. Arg621stop M: RPC/55
17. Male MSH2 Del exon 12–16 CRC/25 H + +/+
12–16 Out of frame deletion M: EC/56
18. Female MSH6 c. 649–650insT CRC/59 L + + +/−
4 p. Asp217fsX218 EC/65 L + + + P: CRC/78 B: CRC/55
19. Female MSH6 c. 649–650insT DC/51 L + + +/−
4 p. Asp217fsX218 CRC/51 ND ND ND ND S: CRC/43
20. Male MSH6 c. 649–650insT CRC/41 L + + +/−
4 p. Asp217fsX218 M: BTC/82
21. Female MSH6 c. 649–650insT CRC/45 H NI NI NI +/−
4 p. Asp217fsX21 CRC/53 H NI NI NI M: GIC/68 S: STC/46
8 STC/62 ND ND ND ND S: EC/50
22. Female MSH6 c. 649–650insT CRC/50 ND ND ND ND +/+
4 p. Asp217fsX218 CRC/83 H + + SN: CRC/37 D: EC/55
23. Male MSH6 c. 2672delT; 2674delT CRC/55 H + +/−
4 p. Ile891fsX899 CRC/55 H + + B: CRC/42
24. Male MSH6 c. 3262–3263insT CRC/38 H + + + −/−
5 p. Phe1088fsX1092
25. Female MSH6 c. 3772C→T 8 cancers† −/−
8 Gln1258sto p. CRC/77 L + +
RPC/63 H ND ND ND

ACII, Amsterdam criteria II; BLC, bladder cancer; BTC, biliary tract cancer; C, DNA changes; CRC, colorectal cancer; D, daughter; DC, duodenal cancer; EC, endometrial cancer; FH, first‐degree family history for HNPCC‐associated tumours; GIC, gastrointestinal cancer; HNPCC, hereditary non‐polyposis colorectal cancer; IHC, immunohistochemistry; M, mother; MSI, microsatellite instability; ND, not done; NI, not interpretable; OC, ovarian cancer; P, father; P, protein changes; RPC, renal pelvic cancer; S, sibling; SD, splicing donor site; SN, son; STC, stomach cancer; UC, ureteric cancer.

*This patient also carried an MSH2 missense mutation.

†Other cancers in this patient were OC/49, CRC/55, EC/57, UC/65, UC/77 and CRC/77.