Table 4.
Gene | Size (aa) | PC/BB function | Domains | Animal mutant |
---|---|---|---|---|
NPHP1 | 732 | BB localization; Interaction w/NPHP2-4, AHI1 | SH3 | M114 |
RPGRIP1L | 1315 | PC defects; BB and PC localization; Interaction w/NPHP4 | C2, CC, RID | M99 |
CEP290 | 2481 | BB localization | CC, SMC, more | no |
TMEM67/MKS3 | 995 | PC defects; BB and PC localization; Interaction w/MKS1 | 7TM, cysteine rich | M108 R70 |
AHI1 | 1196 | BB localization; Interaction w/NPHP1 | CC, WD40, SH3 | no |
ARL13B | 428 | PC defects; PC localization | CC, GTP, proline rich | M96 Z9 |
CC2D2A | 1620 | BB localization; Interaction w/CEP290, IFT88 | CC | Z14 |
aa=amino acid; BB=basal body; C2=Protein kinase C Ca2+ binding domain; CC=coiled-coil; GTP=GTP-binding domain; M = Mouse; PC=primary cilium; R = Rat; RID= RPGR interacting domain; SH3=src homology domain; SMC=Structural Maintenance of Chromosomes chromosome segregation ATPase; TM=Transmembrane domain; Z=Zebrafish;