Table 3. Recurrent CNVs and clinical features in ASD, SZ and MR patients.
Table 3a | |||||||||||
---|---|---|---|---|---|---|---|---|---|---|---|
Patients ID | CNV | Last outer margin (bp) | First inner margin (bp) | Last inner margin (bp) | First outer margin (bp) | genes involved | type | Confirmation | transmission | ||
diagnosis | chromosomal location | Size | |||||||||
113 | SZ | Xp11.4 | 56 kb | 38,326,267 | 38,376,483 | 38,432,836 | 38,549,143 | TSPAN7 | dup | QMPSF, a-CGH | unknown |
313 | SZ | 8p23 | 110 kb | 1,436,299 | 1,481,035 | 1,590,831 | 1,642,837 | DLGAP2 | dup | QMPSF, a-CGH | unknown |
185 | SZ | 15q13 | 994 kb | 26,999,744 | 27,000,694 | 27,994,706 | 28,109,371 | APBA2, TJP1, NDNL2 | dup | QMPSF, a-CCH | unknown |
144.1 | SZ | AFF | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | unknown* | |||
223 | SZ | 2p16.3 | 107 kb | 50,704,195 | 51,006,556 | 51,114,057 | 51,433,167 | NRXN1alpha exons 1,2 | del | QMPSF, a-CGH | unknown |
220 | SZ | 2p16.3 | <532 kb | 50,172,024 | 50,420,164 | 50,420,164 | 50,704,195 | NRXN1alpha/beta | del | QMPSF, a-CGH | unknown |
33 | SZ | 16p11 | 500 kb | DOC2A and 24 genes | dup | QMPSF | maternally inherited** | ||||
136 | SZ | 16p11 | 500 kb | DOC2A and 24 genes | dup | QMPSF | de novo | ||||
146 | SZ AFF | 16p11 | 500 kb | DOC2A and 24 genes | dup | QMPSF | unknown | ||||
151 | SZ | 17q21 | 627 kb | 40,869,151 | 41,073,486 | 41,700,762 | 42,143,048 | MAPT and 2 genes | dup | QMPSF, a-CGH | unknown |
T 35 | autism | 2p16.3 | <427 kb | 51,006,556 | 51,114,057 | 51,114,057 | 51,433,167 | NRXN1alpha exons 1,2 | del | QMPSF, a-CGH, FISH | paternally inherited |
45431 | autism | 2p16.3 | 107 kb | 50,704,195 | 51,006,556 | 51,114,057 | 51,433,167 | NRXN1alpha exons 1,2 | del | QMPSF, a-CGH | maternally inherited |
47604 | autism | 22q13 | 2,26 Mb | 47,124,905 | 47,265,476 | 49,525,071 | --------------- | SHANK3 and 28 genes | del | QMPSF, a-CGH | de novo |
Si22 | autism | 22q13 | ND | SHANK3 | del | QMPSF, MLPA | de novo | ||||
60478 | autism | 15q11-q13 | 4 Mb | GABRA5, GABRB3, GABRG3 and 17 genes | dup | QMPSF, FISH | de novo¶ | ||||
T 34 | autism | Xq25 | 1,42 Mb | 120,669,107 | 120,746,477 | 122,166,142 | 122,316,448 | GRIA3 exons 1-4 | dup | QMPSF, a-CGH, FISH | maternally inherited |
12746 | HFA | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | paternally inherited | ||||
12452 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | paternally inherited | ||||
13899 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | unknown | ||||
44737 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | paternally inherited | ||||
45435 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | unknown | ||||
45856 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | maternally inherited | ||||
46261 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | paternally inherited | ||||
47766 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | paternally inherited | ||||
Si30 | autism | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | maternally inherited | ||||
44813 | HFA | 15q13 | 3,8 Mb | 26,198,996 | 26,999,744 | 30,796,716 | 30,812,300 | APBA2, CHRNA7 and 16 genes | dup | QMPSF, a-CGH | maternally inherited |
12363 | MR | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | maternally inherited | ||||
11780 | MR | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | paternally inherited | ||||
9680 | MR | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | maternally inherited | ||||
14684 | MR | 22q11 | 350 kb | PRODH, DGCR6 | del | QMPSF | maternally inherited | ||||
11695 | MR | 2p16.3 | <427 kb | 51,006,556 | 51,114,057 | 51,114,057 | 51,433,167 | NRXN1alpha exon 1 | del | QMPSF, a-CGH | maternally inherited**** |
14921 | MR | 16p11 | 500 kb | DOC2A and 24 genes | del | QMPSF, FISH | de novo | ||||
10417 | MR | 16p11 | 500 kb | DOC2A and 24 genes | del | QMPSF, FISH | maternally inherited | ||||
13165 | MR | 16p11 | 500 kb | DOC2A and 24 genes | dup | QMPSF, FISH | maternally inherited | ||||
14390 | MR | 16p11 | 500 kb | DOC2A and 24 genes | del | QMPSF, FISH | de novo*** | ||||
13907 | MR | 15q13 | 1,57 Mb | 28,109,371 | 28,725,507 | 30,298,096 | 30,701,373 | CHRNA7 and 5 genes | del | QMPSF, a-CGH | unknown |
11919 | MR | 15q13 | 1,57 Mb | 28,109,371 | 28,725,507 | 30,298,096 | 30,701,373 | CHRNA7 and 5 genes | del | QMPSF, a-CGH | unknown |
9930 | MR | 15q13 | 1,57 Mb | 28,109,371 | 28,725,507 | 30,298,096 | 30,701,373 | CHRNA7 and 5 genes | del | QMPSF, a-CGH | de novo |
12988 | MR | 8p23 | 3 Mb | DLGAP2 and 23 genes | del | QMPSF, HRK | de novo |
Table 3b | |||||||
---|---|---|---|---|---|---|---|
Patients ID | diagnosis | sex | age (y) | family history | CNV | Clinical features | |
Cognitive features | Associated features | ||||||
113 | SZ | M | 52 | sporadic | dup(Xp11.4) | IQ, 105 | |
313 | SZ | M | 32 | familial | dup(8p23) | IQ, 67 | D |
185 | SZ | M | 48 | sporadic | dup(15q13) | IQ, 73 | |
144.1 | SZ AFF | F | 42 | familial | del(22q11) | IQ, 48 | |
223 | SZ | M | 38 | sporadic | del(2p16.3) | IQ, 94 | |
220 | SZ | M | 25 | unknown | del(2p16.3) | NA | |
33 | SZ | F | 53 | familial | dup(16p11) | IQ, 56 | |
136 | SZ | F | 41 | sporadic | dup(16p11) | IQ, 75 | |
146 | SZ AFF | M | 32 | familial | dup(16p11) | IQ, 95 | |
151 | SZ | M | 53 | sporadic | dup(17q21) | IQ, 90 | |
T 35 | autism | F | 38 | sporadic | del(2p16.3) | IQ, 66 | |
45431 | autism | M | 10 | sporadic | del(2p16.3) | NA | |
47604 | autism | M | 8 | sporadic | del(22q13) | IQ<40 | |
Si22 | autism | M | 9 | sporadic | del(22q13) | IQ<40 | D, E |
60478 | autism | M | 15 | sporadic | dup(15q11-q13) | IQ<40 | E |
T 34 | autism | M | 10 | sporadic | dup(Xq25) | NA | |
12746 | HFA | M | 6 | sporadic | del(22q11) | IQ, 74 | |
12452 | autism | F | 8 | sporadic | del(22q11) | IQ<40 | |
13899 | autism | M | 11 | sporadic | del(22q11) | IQ<40 | |
44737 | autism | M | 7 | sporadic | del(22q11) | IQ<40 | |
45435 | autism | F | 31 | sporadic | del(22q11) | IQ<40 | |
45856 | autism | M | 38 | sporadic | del(22q11) | IQ<40 | |
46261 | autism | F | 11 | sporadic | del(22q11) | NA | |
47766 | autism | M | 8 | sporadic | del(22q11) | NA | |
Si30 | autism | F | 5 | sporadic | del(22q11) | IQ<40 | D, E |
44813 | HFA | M | 8 | familial | dup(15q13) | NA | |
12363 | MR | M | 11 | sporadic | del(22q11) | Mild MR | D |
11780 | MR | M | 3 | sporadic | del(22q11) | Mod MR | D |
9680 | MR | F | 11 | familial | del(22q11) | Mod MR | D |
14684 | MR | M | 6 | familial | del(22q11) | DLD | |
11695 | MR | F | 10 | familial | del(2p16.3) | Mod MR | |
14921 | MR | M | 4 | familial | del(16p11) | Mild MR | D |
10417 | MR | M | 14 | familial | del(16p11) | Mild MR | IUGR, D |
13165 | MR | F | 4 | sporadic | dup(16p11) | Mild MR | D |
14390 | MR | F | 9 | familial | del(16p11) | DLD | |
13907 | MR | F | 9 | sporadic | del(15q13) | Mild MR | M, D |
11919 | MR | F | 7 | familial | del(15q13) | Mild MR | |
9930 | MR | M | 12 | familial | del(15q13) | Mild MR | D |
12988 | MR | M | 8 | sporadic | del(8p23) | Mild MR | M, D, E |
a: diseases associated CNVs, b: clinical features of patients with CNVs, M: male; F: female, HFA: High-functioning autism, SZ: schizophrenia, SZ AFF: schizoaffective disorder, MR: mental retardation, Mod: moderate, DLD: developmental learning disorder, Del: deletion; dup: duplication, HRK: High resolution karyotype, D: dysmorphism; E: epilepsy; M: microcephaly; IUGR: intrauterine growth retardation, NA: not assessed
deletion also present in a sibling with schizophrenia
duplication present in a schizophrenic and a healthy sibling, and not present in a schizoaffective sibling
deletion not present in a sibling with mental retardation
deletion present in the proband and an affected sibling
maternally derived