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. Author manuscript; available in PMC: 2017 Aug 11.
Published in final edited form as: Cell Rep. 2017 Jul 11;20(2):384–396. doi: 10.1016/j.celrep.2017.06.045

Figure 4. Ciliogenesis is abnormal in photoreceptors of retinal organoids derived from LCA-iPSCs.

Figure 4

(A) Generation of optic cups from skin biopsy. Scale bars, iPSCs (left) 250μm, iPSC-derived optic cup (right) 200 μm. (B) Representative images of ciliary structures in iPSC-derived optic cups: cilia (I); ciliary vesicle, CV (II); docked MC (III-V); intracellular cilia (VI). Scale bar, 500 nm. (C) Classification of MC and ciliary structures in iPSC-derived optic cups at day 200 analyzed by transmission electron microscopy (TEM); Ctrl-1 (total=19), LCA-2A (total=23), LCA-2F (total=14), from LCA-1 (total=14).