Table 2.
Baseline characteristics of male patients with the classic phenotype
| Male patients with the classic phenotype | ||||||||||||||
|---|---|---|---|---|---|---|---|---|---|---|---|---|---|---|
| 1 | 2 | 3 | 4 | 5 | 6 | 7 | 8 | 9 | 10 | 11 | 12 | 13 | 14 | |
| Variant (amino acid change) | p.I253T | p.I253T | p.C174R | p.G144V | p.D322E | p.G325R | p.Y216C | p.G183D | p.L243F | p.D55V; p.Q57L | p.R301Q | p.G373S | p.P259R | p.P259R |
| Baseline information | ||||||||||||||
| Age (years) | 62 | 61 | 27 | 35 | 60 | 16 | 34 | 35 | 45 | 25 | 56 | 48 | 45 | 45 |
| Weight (kg) | 74 | 58 | 92.7 | 66.5 | 97.07 | 64 | 90.5 | 70 | 67 | 100.6 | 77.6 | 111.2 | 101.8 | 62.7 |
| Time since Fabry diagnosis (years) | 4.6 | 0.3 | 2.6 | 13.4 | 2.4 | 0.4 | 6.2 | 23.9 | 9.1 | 2.6 | 0.6 | 0.5 | 9.9 | 8.9 |
| Previous use of ERT | Yes | No | No | No | No | No | Yes | Yes | Yes | No | No | No | Yes | Yes |
| Blood pressure (SBP/DBP, mm Hg) | 120/80 | NA | 120/70 | 110/63 | 136/84 | 130/70 | 130/90 | 125/62 | 117/63 | 137/96 | 122/94 | 119/66 | 140/80 | 110/70 |
| Urine protein (mg/24 hours) | 331 | 1900 | 1584 | 240 | 918 | 242 | 400 | 150 | 161 | 198 | 2351 | 602 | 335 | 1909 |
| eGFRCKD-EPI (mL/min/1.73 m2) | 86.78 | 53.79 | 44.12 | 104.9 | 41.36 | 151.35 | 119.22 | 109.68 | 102.24 | 98.08 | 55.71 | 64.55 | 105.36 | 86.34 |
| LVMi (g/m2) | 176.18 | 142.78 | 77.36 | 114.93 | 140.79 | 77.86 | 102.06 | 101.77 | 105.02 | 83.42 | 137.47 | 121.68 | 115.86 | 105.77 |
| Urine GL-3 (ng/mg creatinine) | 1975 | 4063.6 | 1090 | 2176.2 | 4163.6 | 2119.2 | 3418.9 | 641.4 | 4196.6 | 750.9 | 1002.4 | 847.6 | 2548.6 | 5245.9 |
| Plasma lyso-Gb3 (nmol/L) | NA | NA | NA | 119.7 | 81.7 | NA | 128 | NA | 109 | 92.2 | NA | NA | 113.3 | 53.3 |
| GSRS-D | 1 | 1 | 1 | 4 | 2 | 4.7 | 1.3 | 1 | 1 | 2.7 | 1 | 3.3 | 4 | 6 |
| WBC α-Gal A activity (4 MU/h/mg) | 0.63 | 0.58 | 0.28 | 0.05 | 0.2 | 0.07 | BLQ | 0.04 | 0.19 | BLQ | 0.42 | 0.29 | 0.6 | 0.44 |
| Use of ACEI/ARB/RI | Yes | No | Yes | No | No | No | No | Yes | Yes | No | Yes | Yes | No | No |
| Medical history a | ||||||||||||||
| Acroparesthesia | No | No | No | Yes | No | No | No | Yes | Yes | No | No | No | No | No |
| Angiokeratoma | No | No | No | No | Yes | No | Yes | Yes | Yes | Yes | No | Yes | Yes | Yes |
| Cornea verticillata | No | No | No | No | No | No | No | No | Yes | No | No | No | No | No |
| Cardiac eventb | Yes | No | Yes | Yes | Yes | No | No | Yes | Yes | Yes | Yes | Yes | Yes | Yes |
| TIA/stroke event | Yes | No | No | No | Yes | No | No | No | No | No | No | No | No | Yes |
| Hearing loss | Yes | No | No | Yes | Yes | No | No | Yes | Yes | No | No | No | No | Yes |
| Hypertension | No | No | Yes | No | Yes | No | No | No | No | No | No | Yes | No | No |
| Hypohidrosis | No | No | No | Yes | No | Yes | Yes | Yes | No | Yes | No | No | No | No |
| GI symptomsc | No | No | Yes | Yes | Yes | Yes | Yes | No | No | Yes | Yes | Yes | No | Yes |
ACEI angiotensin-converting-enzyme inhibitor, ARB angiotensin II receptor blocker, BLQ below the limit of quantification, DBP diastolic blood pressure, eGFRCKD-EP estimated glomerular filtration rate using the Chronic Kidney Disease Epidemiology Collaboration equation, ERT enzyme replacement therapy, GI gastrointestinal, GSRS-D Gastrointestinal Symptom Rating Scale diarrhea domain, LVMi left ventricular mass index, NA not assessed, RI renin inhibitor, SBP systolic blood pressure, TIA transient ischemic attack, WBC white blood cell.
a“Yes” indicates reported and “No” indicates not reported. However, medical history may not have been completely reported; therefore, “No” does not necessarily indicate absence of the complication.
bCardiac events include left ventricular hypertrophy, heart failure, heart valve regurgitation, myocardial infarction, bradycardia, right bundle branch block, atrial fibrillation, and tachycardia.
cGI symptoms include diarrhea, nausea, vomiting, gastroesophageal reflux disease, and abdominal pain/distension.