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. 2018 Jun 7;52(2):71–78. doi: 10.14744/SEMB.2017.51422

Table 1.

Monogenic subtypes of neonatal diabetes mellitus

Gene Locus Hereditary Other clinical features
Abnormal pancreatic development

PLAGL1 6q24 variable TNDM±macroglossia±umbilical hernia
ZFP57 6p22.1 OR TNDM (multiple hypomethylation syndrome) ± macroglossia ± umbilical defects ± congenitalheart disease
PDX1 13q12.1 OR PNDM+pancreatic agenesis (steatorrhea)
PTF1A 10p12.3 OR PNDM + pancreatic agenesis (steatorrhea) + cerebellar hypoplasia/aplasia + central respiratory dysfunction
HNF1B 17cen-q21.3 OD TNDM + pancreatic hypoplasia and renal cysts
RFX6 6q22.1 OR PNDM + intestinal atresia+gallbladder agenesis
GATA6 18q11.1-q11.2 OD PNDM + congenital cardiac defects + biliary anomalies
GLIS3 9p24.3-p23 OR PNDM + congenital hypothyroidism + glaucoma + hepatic fibrosis + renal cysts
NEUROG3 10q21.3 OR PNDM + enteric anendocrinosis, malabsorptive diarrhea
NEUROD1 2q32 OR PNDM + cerebellar hypoplasia + visual impairment + deafness
PAX6 11p13 OR PNDM + microphthalmia + cerebral malformation
Abnormal Β-cell function

KCNJ11 11p15.1 Spontaneous, OD PNDM/TNDM ± DEND
ABCC8 11p15.1 Spontaneous, OD,OR TNDM/PNDM ± DEND
INS 11p15.1 OR Isolated PNDM or TNDM
GCK 7p15-p13 OR Isolated PNDM
SLC2A2(GLUT2) 3q26.1-q26.3 OR Fanconi-Bickel syndrome PNDM + hypergalactosemia, hepatic dysfunction
SLC19A2 1q23.3 OR Roger’s Syndrome PNDM ± Thiamine-responsive megaloblastic anemia, sensorineural deafness
Β-cell destruction

INS 11p15.1 Spontaneous, OD Isolated PNDM
EIF2AK3 2p12 OR Wolcott–Rallison syndrome PNDM + skeletal dysplasia + recurrent hepatic dysfunction
IER3IP1 18q12 OR PNDM + microcephaly + lissencephaly + epileptic encephalopathy
FOX3P Xp11.23-p13.3 X-related, OR IPEX syndrome (autoimmune enteropathy, eczema, autoimmune hypothyroidism, increased IgE)
WFS1 4p16.1 OR PNDM + optic atrophy + diabetes insipidus + deafness

*TNDM: temporary neonatal diabetes mellitus ** PNDM: permanent neonatal diabetes mellitus.