Antibodies |
|
|
Anti-Lipoic acid |
Millipore |
437695-100UL; RRID:AB_212120 |
Anti-LIPT1 |
Sigma-Aldrich |
AV48784; RRID:AB_1852908 |
Anti-DLAT |
Cell Signaling |
#12362; RRID:AB_2797893 |
Anti-DLAT |
Santa Cruz |
sc-271534; RRID:AB_10649809 |
Anti-DLST |
Cell Signaling |
#5556; RRID:AB_10695157 |
Anti-DBT |
GeneTex |
GTX113412; RRID:AB_2036741 |
Anti-p-PDHA1(Ser293) |
Millipore |
ABS204; RRID:AB_11213668 |
Anti-PDHA1 |
Cell Signaling |
#3205; RRID:AB_2162926 |
Anti-ACTB |
Sigma-Aldrich |
A3854; RRID:AB_262011 |
Anti-GAPDH |
Cell Signaling |
#8884; RRID:AB_11129865 |
Biological Samples |
|
|
Patients’ blood samples |
This paper |
N/A |
Patient’s skin biopsies |
This paper |
N/A |
Chemicals, Peptides, and Recombinant Proteins |
|
|
Puromycin |
ThermoFisher |
A1113803 |
Etomoxir sodium salt hydrate |
Sigma-Aldrich |
E1905 |
α-Ketoglutarate |
Sigma-Aldrich |
K1128 |
Citrate |
Sigma-Aldrich |
251275 |
Fumarate |
Sigma-Aldrich |
F19353 |
Malate |
Sigma-Aldrich |
240176 |
Succinate |
Sigma-Aldrich |
S3674 |
L-Aspartate |
Sigma-Aldrich |
A7219 |
Adenosine |
Sigma-Aldrich |
A9251 |
Guanosine |
Sigma-Aldrich |
G6264 |
Uridine |
Sigma-Aldrich |
U3003 |
[U-13C5]Glutamine |
Cambridge Isotope Laboratories |
CLM-1822 |
[U-13C6]Glucose |
Cambridge Isotope Laboratories |
CLM-1396 |
[1-14C]Pyruvate |
PerkinElmer |
NEC255050UC |
L-[U-14C]Valine |
PerkinElmer |
NEC291EU050UC |
3H2O |
PerkinElmer |
6004052 |
Critical Commercial Assays |
|
|
Kit Lenti-Smart INT |
Invivogen |
ItIns-10 |
Kit mammalian mitochondria isolation |
BioVision |
K288 |
Kit PDH activity colorimetric assay |
BioVision |
K679 |
Deproteinizing Sample Preparation Kit |
BioVision |
K808 |
Kit PicoProbeAcetyl-CoA Fluorometric Assay |
BioVision |
K317 |
Kit Q5 Site-Directed Mutagenesis Kit |
NEB |
E0554S |
Kit CellTiter-Glo luminescent cell viability assay |
Promega |
G7572 |
Deposited Data |
|
|
Human LIPT1 mutation N44S |
ClinVar |
SCV000588895 |
Human LIPT1 mutation S292X |
ClinVar |
SCV000588895 |
Experimental Models: Cell Lines |
|
|
Patient-derived fibroblast and ctrl-4917 control fibroblast |
This paper |
N/A |
Primary normal human neonatal fibroblasts |
ATCC |
PCS-201-010 |
Primary normal human adult fibroblasts |
ATCC |
PCS-201-012 |
Detroit 551 |
ATCC |
CCL-110 |
BJ |
ATCC |
CRL-2522 |
H460 |
ATCC |
HTB-177 |
Experimental Models: Organisms/Strains |
|
|
B6C3F1/J mice |
The Jackson Laboratory |
100010 |
Lipt1N44S/+ mice |
This paper |
N/A |
Oligonucleotides |
|
|
Genotyping primer LIPT1-N44S forward: 5′-AAAGCCAAAAGCAACTGCAC-3′ |
This paper |
N/A |
Genotyping primer LIPT1-N44S reverse: 5′-GCCAAGGATTTTGATGCCTA-3′ |
This paper |
N/A |
Genotyping primer LIPT1-S292X forward: 5′-AAACCCAACGGATGAGACAC-3′ |
This paper |
N/A |
Genotyping primer LIPT1-S292X reverse: 5′-TGTTTAGTTTGTGGTCTTGTGGA-3′ |
This paper |
N/A |
Cloning primer LIPT1 forward: 5′-CCGGCGATCGCATGCTGATCCCATTTTC –3′ |
This paper |
N/A |
Cloning primer LIPT1 reverse: 5′-CGGACGCGTCATTATTCCCTTAATTTTTTC-3′ |
This paper |
N/A |
Cloning primer LIPT1-S292X reverse: 5′-CGGACGCGTCTGTTCATATAACACATGAAAGG-3′ |
This paper |
N/A |
Mutagenesis primer LIPT1-N44S forward: 5′-GTCTATCAAAGTCTGGCTGTG-3′ |
This paper |
N/A |
Mutagenesis primer LIPT1-N44S reverse: 5′-ATCATTGGAAATTGACTGTAAAATG-3′ |
This paper |
N/A |
Genotyping primer Lipt1-N44S forward: 5′-AAGAAGGTCTGGACCCTTTGA-3′ |
This paper |
N/A |
Genotyping primer Lipt1-N44S reverse: 5′-GCCAGTTTGATTCCTTCCTG-3′ |
This paper |
N/A |
sgRNA target sequence of Lipt1 for CRISPR knock-in of N44S: 5′-CTTCTAGATGTATGTGGTCGTGG-3′ |
This paper |
N/A |
HR template single-strand oligo for CRISPR knock-in of N44S: 5′-CTTTGTCAGCACAAGGTCCCAGCAGCTGGCTTTAAAAGCCCACCCACACATGGGCTCATTTTACAGTCGATCTCCAATGATGTATATGAAAGTCTGGCTTTTGAAGACTGGATTCATGACCACATACATCTCGAAGGCAAGCCGATTCTTTTCCTTTGGAGAAATTCTCCTTCTGTCGTCATC-3′ |
This paper |
N/A |
Recombinant DNA |
|
|
pLOX-TERT-iresTK |
Addgene |
12245 |
pLenti-EF1a-C-Myc-DDK-IRES-Puro |
OriGene |
PS10085 |
pLenti-EF1a-C-Myc-DDK-IRES-Puro-LIPT1-WT |
This paper |
N/A |
pLenti-EF1a-C-Myc-DDK-IRES-Puro-LIPT1-N44S |
This paper |
N/A |
pLenti-EF1a-C-Myc-DDK-IRES-Puro-LIPT1-S292X |
This paper |
N/A |
Software and Algorithms |
|
|
MultiQuant software v2.1 |
Applied Biosystems |
N/A |
SIMCA-P v13.0.1 |
Umetrics |
N/A |
Heatmap3 |
https://cran.r-project.org/web/packages/heatmap3/index.html |
N/A |
MetaboAnalyst 3.0 |
http://www.metaboanalyst.ca/ |
N/A |
HOPE-CMBI |
http://www.cmbi.ru.nl/hope/ |
N/A |
PyMol |
https://pymol.org/2/ |
N/A |