Table 1.
Pathogenic or likely pathogenic variants found in Korean or Japanese patients with Pompe disease or in general population databases.
Variant | Korean Patients | Japanese Patients | General Population Databases, MAF | |||||
---|---|---|---|---|---|---|---|---|
Allele Count | [Ref] (HT/HM) | Allele Count | [Ref] (HT/HM) | KRGDB 1 | jMorp 2 | gnomAD 3, East Asian | gnomAD 3, Global | |
c.-32-13T>G | 0 | 0 | 0.000342 | 0 | 0.000207 | 0.003401 | ||
c.2T>C | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0 | |
c.118C>T (p.Arg40 *) | 1 | [20] (1/0) | 1 | [28] (1/0) | 0 | 0 | 0.000050 | 0.000014 |
c.169C>T (p.Gln57 *) | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0 | |
c.307T>C (p.Cys103Arg) | 0 | 0 | 0 | 0.000060 | 0 | 0 | ||
c.309C>A (p.Cys103 *) | 0 | 2 | [29] (0/1) | 0 | 0 | 0 | 0 | |
c.483dup (p.Lys162Glnfs*15) | 0 | 2 | [30] (2/0) | 0 | 0 | 0 | 0 | |
c.546G>A (p.Thr182=) | 0 | 0 | 0 | 0.000179 | 0.000102 | 0.000030 | ||
c.546G>T (p.Thr182=) | 2 | [22] (1/0), [25] (1/0) | 27 | [28] (6/5), [34] (0/2), [35] (2/1), [36] (1/0), [37] (0/1) | 0 | 0.000119 | 0 | 0 |
c.547-1G>C | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0 | |
c.569G>A (p.Arg190His) | 0 | 1 | [28] (1/0) | 0 | 0.000060 | 0 | 0.000016 | |
c.655G>A (p.Gly219Arg) | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0.000018 | |
c.670C>T (p.Arg224Trp) | 0 | 1 | [31] (1/0) | 0 | 0 | 0 | 0.000022 | |
(c.752C>T; c.761C>T) ((p.Ser251Leu; p.Ser254Leu) | 0 | 2 | [28] (1/0) | 0.005476 | 0.001850 | 0.002759 | 0.000195 | |
c.756_757insT (p.Pro253Serfs*77) | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0 | |
c.796C>T (p.Pro266Ser) | 1 | [26] (1/0) | 2 | [28] (2/0) | 0 | 0 | 0 | 0 |
c.841C>T (p.Arg281Trp) | 0 | 0 | 0 | 0.000060 | 0 | 0.000205 | ||
c.875A>G (p.Tyr292Cys) | 4 | [18] (1/0), [19] (1/0), [21] (1/0), [23] (1/0) | 0 | 0 | 0 | 0 | 0.000008 | |
c.1156C>T (p.Gln386 *) | 1 | [23] (1/0) | 0 | 0 | 0 | 0 | 0 | |
c.1225dup (p.Asp409Glyfs*97) | 1 | [20] (1/0) | 0 | 0 | 0 | 0 | 0 | |
c.1309C>T (p.Arg437Cys) | 3 | [18] (1/0), [19] (1/0), [25] (1/0) | 12 | [28] (6/0), [33] (2/0), [38] (1/0), [39] (0/1), [40] (1/0) | 0 | 0.000060 | 0 | 0.000008 |
c.1316T>A (p.Met439Lys) | 14 | [18] (4/0), [19] (1/0), [20] (1/0), [22] (1/0), [23] (1/0), [24] (1/0), [25] (3/0), [26] (2/0) | 3 | [28] (0/1), [35] (1/0) | 0.001027 | 0 | 0.000384 | 0.000028 |
c.1322_1326+9del | 2 | [18] (1/0), [19] (1/0) | 0 | 0 | 0 | 0 | 0 | |
c.1447G>A (p.Gly483Arg) | 0 | 0 | 0 | 0.000060 | 0 | 0.000008 | ||
c.1579_1580del (p.Arg527Glyfs*3) | 2 | [19] (1/0), [20] (1/0) | 0 | 0 | 0 | 0 | 0.000004 | |
c.1582_1583del (p.Gly528Leufs*2) | 1 | [18] (1/0) | 0 | 0 | 0 | 0 | 0 | |
c.1585_1586delinsGT (p.Ser529Val) | 0 | 7 | [32] (2/2), [41] (1/0) | 0 | 0 | 0 | 0 | |
c.1696T>C (p.Ser566Pro) | 0 | 4 | [28] (2/0), [30] (2/0) | 0 | 0 | 0 | 0 | |
c.1735G>A (p.Glu579Lys) | 0 | 2 | [28] (1/0), [42] (1/0) | 0 | 0 | 0 | 0.000007 | |
c.1798C>T (p.Arg600Cys) | 0 | 20 | [28] (7/0), [31] (1/0), [32] (7/1), [35] (2/0), [36] (1/0) | 0 | 0.000239 | 0 | 0.000004 | |
c.1822C>T (p.Arg608 *) | 6 | [18] (2/0), [19] (2/0), [22] (1/0), [24] (1/0) | 4 | [28] (1/1), [35] (1/0) | 0 | 0 | 0.000051 | 0.000018 |
c.1826dup (p.Tyr609 *) | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0.000008 | |
c.1857C>G (p.Ser619Arg) | 7 | [20] (1/0), [21] (1/0), [23] (2/0), [24] (1/0), [25] (1/0), [26] (1/0) | 15 | [28] (4/3), [31] (0/1), [33] (0/1), [42] (1/0) | 0.000342 | 0.000418 | 0 | 0 |
c.1935C>A (p.Asp645Glu) | 0 | 3 | [32] (1/1) | 0 | 0 | 0.001729 | 0.000124 | |
c.1979G>A (p.Arg660His) | 0 | 2 | [31] (2/0) | 0 | 0 | 0 | 0.000037 | |
c.2014C>T (p.Arg672Trp) | 0 | 0 | 0 | 0.000060 | 0 | 0.000008 | ||
c.2015G>A (p.Arg672Gln) | 5 | [20] (1/0), [24] (2/0), [25] (1/0), [26] (1/0) | 8 | [32] (2/2), [43] (0/1) | 0.000343 | 0 | 0.000111 | 0.000021 |
c.2171C>A (p.Ala724Asp) | 3 | [18] (1/0), [19] (1/0), [25] (1/0) | 0 | 0 | 0 | 0 | 0 | |
c.2177C>G (p.Pro726Arg) | 0 | 2 | [28] (1/0), [40] (1/0) | 0 | 0 | 0 | 0 | |
c.2297A>G (p.Tyr766Cys) | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0.000025 | |
c.2238G>C (p.Trp746Cys) | 5 | [19] (1/0), [22] (1/0), [24] (1/0), [25] (2/0) | 0 | 0.000685 | 0 | 0.000351 | 0.000308 | |
c.2238G>T (p.Trp746Cys) | 0 | 0 | 0 | 0.000119 | 0 | 0 | ||
c.2326C>T (p.Gln776 *) | 0 | 2 | [33] (2/0) | 0 | 0 | 0 | 0 | |
c.2407_2413del (p.Gln803 *) | 1 | [23] (1/0) | 0 | 0 | 0 | 0 | 0 | |
c.2481+1G>A | 0 | 1 | [28] (1/0) | 0 | 0 | 0 | 0 | |
c.2647-7G>A | 0 | 0 | 0.000342 | 0.000298 | 0 | 0.000018 |
1 The Korean Reference Genome Database (KRGDB, http://coda.nih.go.kr/coda/KRGDB/index.jsp, accessed on 8 February 2021). 2 The Japanese Multi Omics Reference Panel (jMorp, https://jmorp.megabank.tohoku.ac.jp/202102/variants, accessed on 16 March 2021). 3 The Genome Aggregation Database (gnomAD, https://gnomad.broadinstitute.org/, accessed on 17 March 2021). *, stop codon; Ref, references; HT, heterozygous allele count; HM, homozygous allele count; MAF, minor allele frequency.