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. 2021 Sep 9;12:500. doi: 10.1186/s13287-021-02565-6

Table 2.

Therapeutic HDR gene-editing strategy for genetic disorders using ZFNs, TALENs and Cas9

Disease Nuclease Target locus HDR-gene-editing strategy Delivery route Experimental model References
Sickle cell disease & β-thalassemia ZFNs HBB ZFN mRNA and IDLV/ssODN Electroporation (Harvard apparatus) HSPCs from healthy donor and SCD patient [10]
Cas9 HBB Cas9 RNP and plasmid donor Electroporation (Lonza Nucleofector 4-D) HSPCs from healthy donor and SCD patient [23]
Cas9 mRNA and ssODN Electroporation (Neon transfection system and Lonza 4D Nucleofector) HSPCs from healthy donor [24]
Cas9 mRNA and IDLV Electroporation (ECM 830 Square wave electroporator) HSPCs from SCD patient [53]
Cas9 RNP and ssODN Electroporation (Lonza 4D Nucleofector) HSPCs from healthy donor [22]
Cas9 RNP and ssODN Electroporation (Lonza 4D Nucleofector) HSPCs from healthy donor [54]
Cas9 RNP and plasmid donor Electroporation (Lonza Nucleofector 2b) HSPCs from SCD patient [55]
X-SCID ZFNs IL2RG ZFN mRNA and IDLV Electroporation (Lonza) HSPCs from healthy donor and SCID-X1 patient [57]
ZFN and IDLV Transduction HSPCs from healthy donor [58]
Cas9 Cas9 RNP and AAV6 Electroporation (Lonza nucleofector 4D) HSPCs from SCID-X1 patient [30]
X-linked chronic granulomatous disease Cas9 CYBB Cas9 RNP and ssODN Electroporation (MaxCyte systems) HSPCs from X-CGD patient [29]
Wiskott–Aldrich syndrome Cas9 WAS Cas9 RNP and AAV6 Electroporation/transduction (MaxCyte CTX Flow electroporator) HSPCs from healthy donor and WAS patient [17]
Mucopolysaccharidosis Cas9 CCR5 Cas9 RNP and AAV6 Electroporation/transduction (Lonza nucleofector 4D) HSPCs from healthy donor [34]
Gaucher disease Cas9 CCR5 Cas9 RNP and AAV6 Electroporation/transduction (Lonza 4D nucleofector) HSPCs from healthy donor [59]
Pyruvate Kinase Deficiency TALEN& Cas9 PKLR TALEN plasmid/Cas9 RNP and plasmid donor Electroporation (Lonza AMXA II nucleofection system) HSPCs from healthy donor [27]
IPEX syndrome Cas9 FOXP3 Cas9 RNP and AAV6 Nucleofection/transduction (Lonza 4D nucleofector) HSPCs from healthy donor [32]