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[Preprint]. 2024 Oct 11:2024.10.07.617092. [Version 1] doi: 10.1101/2024.10.07.617092

Linking candidate causal autoimmune variants to T cell networks using genetic and epigenetic screens in primary human T cells

Ching-Huang Ho, Maxwell A Dippel, Meghan S McQuade, Arpit Mishra, Stephan Pribitzer, LeAnn P Nguyen, Samantha Hardy, Harshpreet Chandok, Florence Chardon, Troy A McDiarmid, Hannah A DeBerg, Jane H Buckner, Jay Shendure, Carl G de Boer, Michael H Guo, Ryan Tewhey, John P Ray
PMCID: PMC11482744  PMID: 39416200

Abstract

Genetic variants associated with autoimmune diseases are highly enriched within putative cis -regulatory regions of CD4 + T cells, suggesting that they alter disease risk via changes in gene regulation. However, very few genetic variants have been shown to affect T cell gene expression or function. We tested >18,000 autoimmune disease-associated variants for allele-specific expression using massively parallel reporter assays in primary human CD4 + T cells. The 545 expression-modulating variants (emVars) identified greatly enrich for likely causal variants. We provide evidence that many emVars are mediated by common upstream regulatory conduits, and that putative target genes of primary T cell emVars are highly enriched within a lymphocyte activation network. Using bulk and single-cell CRISPR-interference screens, we confirm that emVar-containing T cell cis -regulatory elements modulate both known and novel target genes that regulate T cell proliferation, providing plausible mechanisms by which these variants alter autoimmune disease risk.

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