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[Preprint]. 2024 Nov 28:2024.11.26.24318007. [Version 1] doi: 10.1101/2024.11.26.24318007

Long-telomeropathy is associated with tumor predisposition syndrome

Patrick Allaire, John Mayer, Luke Moat, Rachel Gabor, Jerry W Shay, Jing He, Chenjie Zeng, Lisa Bastarache, Scott Hebbring
PMCID: PMC11623752  PMID: 39649603

Summary

Telomeres protect chromosomal integrity, and telomere length (TL) is influenced by environmental and genetic factors. While short-telomeres are linked to rare telomeropathies, this study explored the hypothesis that a “long-telomeropathy” is associated with a cancer-predisposing syndrome. Using genomic and health data from 113,861 individuals, a trans-ancestry polygenic risk score for TL (PRS TL ) was developed. A phenome-wide association study (PheWAS) identified 65 tumor traits linked to elevated PRS TL . Using this result, a trans-ancestry phenotype risk score for a long-TL (PheRS LTL ) was develop and validated. Rare variant analyses revealed 13 genes associated with PheRS LTL . Individuals who were carriers of these rare variants had a predisposition for long-TL validating original hypothesis. Most of these genes were new to both cancer and telomere biology. In conclusion, this study identified a novel tumor-predisposing syndrome shaped by both common and rare genetic variants, broadening the understanding of telomeropathies to those with a predisposition for long telomeres.

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