Skip to main content

This is a preprint.

It has not yet been peer reviewed by a journal.

The National Library of Medicine is running a pilot to include preprints that result from research funded by NIH in PMC and PubMed.

medRxiv logoLink to medRxiv
[Preprint]. 2026 Jul 10:2026.06.30.26356693. [Version 1] doi: 10.64898/2026.06.30.26356693

Germline determinants of risk and molecular subtype in young-onset lung cancer

Jaclyn LoPiccolo, Ryan L Collins, Noah Fields, Carter Nakagawa, Kodi Taraszka, Xinan Wang, Li Su, Diane R Koeller, Alison Levine Schwartz, Alicia Charleston Pollaci, Sarah M Young, Victoria G Williamson, Jose A Avila, Emma Voligny, Tom Nguyen, Andy J Pangilinan, Richard M Erwin, Barbara J Gitlitz, Silvia Novello, Geoffrey R Oxnard, Ugonma N Chukwueke, Priscilla K Brastianos, Ayal A Aizer, Mizuki Nishino Hatabu, Narjust Florez, Kevin M Haigis, Eliezer M Van Allen, Jorge J Nieva, Judy E Garber, David C Christiani, Pasi A Jänne, Alexander Gusev
PMCID: PMC13370489  PMID: 42465903

A bstract

Young-onset lung cancer is enriched for never-smoking and oncogene-driven tumors, yet its inherited genetic basis remains poorly defined. We performed germline whole-genome sequencing in 251 young-onset lung cancer cases (median age 37), which we jointly analyzed with never-smoking cases (n=196; median age 68) and cancer-free controls (n=1,883). We identified enrichments of rare deleterious coding variants across 55 cancer-related gene sets, including EGFR/ERBB2 signaling and genes implicated by prior lung cancer GWAS. Exome-wide analyses of rare coding variants affirmed TP53 as a penetrant lung cancer predisposition gene (odds ratio [OR]=36.1, p=1.02×10 -7 ) and discovered two novel exome-wide significant tumor subtype-dependent associations: IREB2 in cases with fusion-driven tumors (p=1.39×10 -6 ) and SMAD6 in fusion-negative tumors (p=2.05×10 -6 ). Structural variants contributed distinct risk, with enrichment in constrained, lung-expressed genes (OR=5.79, p=5.8×10 -5 ) and very large germline deletions being markedly enriched in cases with fusion-driven tumors. Polygenic risk scores for lung cancer were inversely correlated with rare variant burden, consistent with additive risk from rare and common variants. Collectively, these findings delineate a complex germline architecture underlying susceptibility and molecular subtype in young-onset lung cancer.

Full Text Availability

The license terms selected by the author(s) for this preprint version do not permit archiving in PMC. The full text is available from the preprint server.


Articles from medRxiv are provided here courtesy of Cold Spring Harbor Laboratory Preprints

RESOURCES