Skip to main content
Archives of Disease in Childhood logoLink to Archives of Disease in Childhood
. 2000 Jul;83(1):74–75. doi: 10.1136/adc.83.1.74

Early onset of Friedreich's ataxia in a compound heterozygote

M C McGovern 1, M Stewart 1, P Morrison 1, D Webb 1, S Hawkins 1
PMCID: PMC1718374  PMID: 10869006

Abstract

Friedreich's ataxia (FA) is an autosomal recessive condition caused by a GAA trinucleotide repeat expansion in the X25 gene on chromosome 9. We describe an unusual form of "pseudodominant" inheritance to illustrate how a diagnosis of FA in a parent does not preclude the diagnosis in the child.



Full Text

The Full Text of this article is available as a PDF (75.4 KB).

Selected References

These references are in PubMed. This may not be the complete list of references from this article.

  1. Babcock M., de Silva D., Oaks R., Davis-Kaplan S., Jiralerspong S., Montermini L., Pandolfo M., Kaplan J. Regulation of mitochondrial iron accumulation by Yfh1p, a putative homolog of frataxin. Science. 1997 Jun 13;276(5319):1709–1712. doi: 10.1126/science.276.5319.1709. [DOI] [PubMed] [Google Scholar]
  2. Campuzano V., Montermini L., Moltò M. D., Pianese L., Cossée M., Cavalcanti F., Monros E., Rodius F., Duclos F., Monticelli A. Friedreich's ataxia: autosomal recessive disease caused by an intronic GAA triplet repeat expansion. Science. 1996 Mar 8;271(5254):1423–1427. doi: 10.1126/science.271.5254.1423. [DOI] [PubMed] [Google Scholar]
  3. Gray J. V., Johnson K. J. Waiting for frataxin. Nat Genet. 1997 Aug;16(4):323–325. doi: 10.1038/ng0897-383. [DOI] [PubMed] [Google Scholar]
  4. Harding A. E. Friedreich's ataxia: a clinical and genetic study of 90 families with an analysis of early diagnostic criteria and intrafamilial clustering of clinical features. Brain. 1981 Sep;104(3):589–620. doi: 10.1093/brain/104.3.589. [DOI] [PubMed] [Google Scholar]
  5. Harding A. E., Zilkha K. J. 'Pseudo-dominant' inheritance in Friedreich's ataxia. J Med Genet. 1981 Aug;18(4):285–287. doi: 10.1136/jmg.18.4.285. [DOI] [PMC free article] [PubMed] [Google Scholar]
  6. Monrós E., Moltó M. D., Martínez F., Cañizares J., Blanca J., Vílchez J. J., Prieto F., de Frutos R., Palau F. Phenotype correlation and intergenerational dynamics of the Friedreich ataxia GAA trinucleotide repeat. Am J Hum Genet. 1997 Jul;61(1):101–110. doi: 10.1086/513887. [DOI] [PMC free article] [PubMed] [Google Scholar]

Articles from Archives of Disease in Childhood are provided here courtesy of BMJ Publishing Group

RESOURCES